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Case Report

Fatal Balamuthia Amebic Encephalitis in a Healthy Child: A Case Report with Review of Survival Cases

The Korean Journal of Parasitology 2013;51(3):335-341.
Published online: June 30, 2013

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Corresponding author (Yong.P@chula.ac.th)
• Received: January 20, 2013   • Revised: March 4, 2013   • Accepted: March 7, 2013

© 2013, Korean Society for Parasitology and Tropical Medicine

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.

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Fatal Balamuthia Amebic Encephalitis in a Healthy Child: A Case Report with Review of Survival Cases
Korean J Parasitol. 2013;51(3):335-341.   Published online June 30, 2013
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Fatal Balamuthia Amebic Encephalitis in a Healthy Child: A Case Report with Review of Survival Cases
Image Image Image
Fig. 1 Pre- and postoperative imaging studies of the brain. (A) Axial T2-weighted MRI showing a 3.0×4.1×2.5 cm ill-defined infiltrating heterogeneous enhancing mass mainly occupying the right inferior cerebellar hemisphere with perilesional edema causing right tonsillar herniation and mild obstructive hydrocephalus. (B) Follow-up axial CT scan of the brain, 5 days post-operation, showing a hypodense lesion with perilesional vasogenic edema at the right cerebellar vermis and right cerebellar hemisphere, postoperative change.
Fig. 2 Pathology of Balamuthia amebic encephalitis. Multiple amebic trophozoites in the cerebellar lesion are illustrated. The organisms tend to cling around a blood vessel (left side image). Note dense infiltrates of lymphocytes and plasma cells at top. H-E stain, ×400, Bar=50 µm.
Fig. 3 Phylogenetic tree analysis of Balamuthia mandrillaris.
Fatal Balamuthia Amebic Encephalitis in a Healthy Child: A Case Report with Review of Survival Cases
Pub year Age Sex Place Underlying diseases Lesions Method Treatment Outcome Ref 2011 27 M Kidney recipient 21 d CNS:- multiple enhancing lesions, ICA aneurysm Donor autopsy, brain biopsy (other recipient) PCR, IIF+ Pentamidine, sulfadiazine, flucytosine, fluconazole, azithromycin, miltefosine Arm, leg paralysis, CNS: healed aneurysm 6,7 2011 80 F Australia Skin: plaques at limbs & trunk 1 y 2nd skin Bx: cutaneous amebiasis Complete excision, itraconazole, flucytosine, sulfadiazine, azithromycin×7 m, amphotericin B, pentamidine×7 w Complete recovery F/U 18 m 8,9 CNS:1 ring-enhancing mass (frontal lobe) Brain Bx- trophozoites, PCR+ 2010 21 F Lima, Peru Skin: lesions at knee 4 y Skin Bx- trophozoites culture, PCR, IIF+ Surgical resection of small lesions itraconazole, albendazole, amphotericin B×10 m, TMP-SMX×3 m; no improvement amphotericin B, itraconazole, TMP-SMX, albendazole×45d; no improvement clarithromycin, artesunate×2w; no improvement albendazole, fluconazole×7.5 m, miltefosine×7 m Skin & CNS lesions healed F/U>30 m 10 CNS:-1 ring-enhancing lesion (temporal lobe) 2010 2 M CNS: - multiple enhancing lesions Brain Bx trophozoites, IIF+ VP shunt, fluconazole, flucytosine, sulfadiazine, clarithromycin>2 m, Pentamidine, thioridazine<2 m CNS:↓size, no. of lesions, F/U>22 m 11 2008 35 M CA, USA B cell lymphoma CNS: - focal enhancing lesions Serology, PCR + Unknown Doing well 3 m lost F/U 9, 12 2006 8 M Piura, Peru Skin:- plaque on face Albendazole, itraconazole×14 m Skin & CNS healed, F/U>3 y 13 CNS: - multiple focal lesions 2006 10 F Piura, Peru Skin: plaque on face Surgical resection albendazole, itraconazole, TMP-SMX ×6 m No neurological sequelae, F/U 18 m 13 CNS:-2 ring-enhancing lesions (frontal lobe) 2004 72 F NY, USA CNS: - 2 ring-enhancing lesions (frontal and temporal lobes) Brain Bx- trophozoites IIF+ Excisional Bx 1 of 2 lesions pentamidine, sulfadiazine, fluconazole, clarithromycin×unknown duration CNS 2w: slight evolution of lesions, F/U >6 m 14 2003 64 M CA, USA Ankylosing spondylitis, MI, glaucoma, depression Skin:- raised lesion at forearm 2 w Brain Bx- granulomatous vasculitis Biopsy only flucytosine, fluconazole, sulfadiazine× 5 y clarithromycinx 2 y pentamidinex 2 w, trifluoperazine×18 d CNS 5y:- ↓ size of lesions, F/U>5 y 15 CNS:-4 ring-enhancing lesions (parietal and occipital lobes) Review of skin Bx- trophozoites, IIF+ 2003 5 F CA, USA CNS: - 2 ring-enhancing lesions (temporal and parietal lobes) Brain Bx- acute necrotizing inflammation, + trophozoites, IIF+ Partial excision 1 of 2 lesions clarithromycin, fluconazole>2.4 y, flucytosine×2.4 y thioridazine×1.8 y, pentamidine×34 d CNS 2.4 y: -↓edema, F/U>2.4 y 15
Table 1. Summary of demographic characteristics, clinical data, and treatment of the 10 survivors of Balamuthia amebic infection

F, female; M, male; d, day; w, week; m, month; y, year; CNS, central nervous system; PCR, Polymerase chain reaction; Bx, biopsy, IIF, indirect immunofluorescence; ESRD, End stage renal disease; MI, myocardial infarction; ICA, internal carotid artery; VP, ventriculoperitoneal.